PAPILLON-LEFE\'VRE SYNDROME: NEUTROPHIL MOTILITY AND KILLING DEFECT IN A CHILD WITH RECURRENT SEVERE INFECTIONS

Authors

  • ABOLHASAN FARHOUDI From the Department of Clinical Immunology and Allergy, Children's Medical Center, Tehran University of Medical Sciences, Tehran
  • ATHAR MOIN the Department of Dermatology, Shahed University, Tehran, Islamic Republic of Iran.
  • M MOIN From the Department of Clinical Immunology and Allergy, Children's Medical Center, Tehran University of Medical Sciences, Tehran
Abstract:

A case of palmoplantar hyperkeratosis with periodontosis and a history of recurrent severe pyoderma, pneumonia and multiple liver abscesses is described in a 12 year old girl. The patient demonstrated neutrophil dysfunction characterized by decreased random migration and chemotaxis and defective bactericidal activity. The exact immunopathological mechanism for susceptibility to infections in Papillon-Lefe'vre syndrome patients still remains to be determined. However, the mode of clinical presentation, laboratory findings and response to retinoid treatment, all support the speculation of Papillon-Lefe'vre syndrome as a primary immunologic disease with a variable defect in neutrophil motility and bactericidal activity. The pattern of clinical presentations as skin and periodontal lesions alone or with susceptibility to infection in other sites will change accordingly.

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Journal title

volume 11  issue 2

pages  149- 152

publication date 1997-08

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